J Clin Invest. 2013 Nov;123(11):4935-44. doi: 10.1172/JCI69766. Epub 2013 Oct 25.
Exposure to ionizing radiation during childhood markedly increases the risk of developing papillary thyroid cancer. We examined tissues from 26 Ukrainian patients with thyroid cancer who were younger than 10 years of age and living in contaminated areas during the time of the Chernobyl nuclear reactor accident. We identified nonoverlapping somatic driver mutations in all 26 cases through candidate gene assays and next-generation RNA sequencing. We found that 22 tumors harbored fusion oncogenes that arose primarily through intrachromosomal rearrangements. Altogether, 23 of the oncogenic drivers identified in this cohort aberrantly activate MAPK signaling, including the 2 somatic rearrangements resulting in fusion of transcription factor ETS variant 6 (ETV6) with neurotrophic tyrosine kinase receptor, type 3 (NTRK3) and fusion of acylglycerol kinase (AGK) with BRAF. Two other tumors harbored distinct fusions leading to overexpression of the nuclear receptor PPARγ. Fusion oncogenes were less prevalent in tumors from a cohort of children with pediatric thyroid cancers that had not been exposed to radiation but were from the same geographical regions. Radiation-induced thyroid cancers provide a paradigm of tumorigenesis driven by fusion oncogenes that activate MAPK signaling or, less frequently, a PPARγ-driven transcriptional program.
儿童时期接触电离辐射会显著增加罹患甲状腺乳头状癌的风险。我们研究了 26 名 10 岁以下且在切尔诺贝利核反应堆事故期间居住在污染地区的乌克兰甲状腺癌患者的组织样本。通过候选基因检测和下一代 RNA 测序,我们在所有 26 例患者中均发现了非重叠的体细胞驱动突变。我们发现,22 个肿瘤中存在主要通过染色体内重排产生的融合致癌基因。总的来说,本队列中鉴定出的 23 个致癌驱动基因异常激活了 MAPK 信号通路,包括导致转录因子 ETS 变体 6(ETV6)与神经营养酪氨酸激酶受体 3(NTRK3)融合以及酰基甘油激酶(AGK)与 BRAF 融合的 2 个体细胞重排。另外两个肿瘤存在导致核受体 PPARγ 过表达的独特融合。在未接触辐射但来自同一地理区域的另一组儿童甲状腺癌患者的肿瘤中,融合致癌基因的发生率较低。辐射诱导的甲状腺癌为融合致癌基因驱动的肿瘤发生提供了范例,这些致癌基因可激活 MAPK 信号通路,或较少见地激活 PPARγ 驱动的转录程序。