Ferenci P
Department of Internal Medicine IV, Gastroenterology and Hepatology, University of Vienna, Vienna, Austria.
Clin Liver Dis. 1998 Feb;2(1):31-49, v-vi. doi: 10.1016/s1089-3261(05)70362-7.
Wilson's disease is an autosomal, recessive-inherited disorder of impaired biliary copper excretion that results in the accumulation of copper in various organs including the liver, the cornea and the brain. The Wilson's disease gene on chromosome 13 codes for a copper transporting P-type ATPase-ATP7B. More than 60 mutations of this gene have been described. The diagnosis of Wilson's disease is based on clinical findings and laboratory abnormalities and can be made if two of the following symptoms are present: Kayser-Fleischer rings; topical neurologic symptoms; and low serum ceruloplasmin levels. In less typical cases diagnosis requires various other tests of copper metabolism. Effective medical treatment with copper chelators (D-penicillamine, trientine) or zinc results in symptomatic improvement and normal life expectancy. Orthotopic liver transplantation is indicated in advanced cases with hepatic decompensation or in patients with fulminant Wilson's disease.
威尔逊病是一种常染色体隐性遗传的疾病,其特征为胆汁铜排泄受损,导致铜在包括肝脏、角膜和大脑在内的各种器官中蓄积。位于13号染色体上的威尔逊病基因编码一种铜转运P型ATP酶——ATP7B。该基因已发现60多种突变。威尔逊病的诊断基于临床表现和实验室异常情况,如果出现以下两种症状即可确诊:凯-弗环;局部神经症状;血清铜蓝蛋白水平降低。在不太典型的病例中,诊断需要进行各种其他铜代谢测试。使用铜螯合剂(D-青霉胺、曲恩汀)或锌进行有效的药物治疗可使症状改善,预期寿命正常。原位肝移植适用于晚期肝失代偿病例或暴发性威尔逊病患者。