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信号转导子和转录激活子 3(STAT3)突变导致常染色体显性遗传高免疫球蛋白 E 综合征,损害人类 CD8(+) T 细胞记忆形成和功能。

Signal transducer and activator of transcription 3 (STAT3) mutations underlying autosomal dominant hyper-IgE syndrome impair human CD8(+) T-cell memory formation and function.

机构信息

Immunology Research Program, Garvan Institute of Medical Research, Darlinghurst, Australia.

出版信息

J Allergy Clin Immunol. 2013 Aug;132(2):400-11.e9. doi: 10.1016/j.jaci.2013.05.029. Epub 2013 Jul 4.

Abstract

BACKGROUND

The capacity of CD8(+) T cells to control infections and mediate antitumor immunity requires the development and survival of effector and memory cells. IL-21 has emerged as a potent inducer of CD8(+) T-cell effector function and memory development in mouse models of infectious disease. However, the role of IL-21 and associated signaling pathways in protective CD8(+) T-cell immunity in human subjects is unknown.

OBJECTIVE

We sought to determine which signaling pathways mediate the effects of IL-21 on human CD8(+) T cells and whether defects in these pathways contribute to disease pathogenesis in patients with primary immunodeficiencies caused by mutations in components of the IL-21 signaling cascade.

METHODS

Human primary immunodeficiencies resulting from monogenic mutations provide a unique opportunity to assess the requirement for particular molecules in regulating human lymphocyte function. Lymphocytes from patients with loss-of-function mutations in signal transducer and activator of transcription 1 (STAT1), STAT3, or IL-21 receptor (IL21R) were used to assess the respective roles of these genes in human CD8(+) T-cell differentiation in vivo and in vitro.

RESULTS

Mutations in STAT3 and IL21R, but not STAT1, led to a decrease in multiple memory CD8(+) T-cell subsets in vivo, indicating that STAT3 signaling, possibly downstream of IL-21R, regulates the memory cell pool. Furthermore, STAT3 was important for inducing the lytic machinery in IL-21-stimulated naive CD8(+) T cells. However, this defect was overcome by T-cell receptor engagement.

CONCLUSION

The IL-21R/STAT3 pathway is required for many aspects of human CD8(+) T-cell behavior but in some cases can be compensated by other signals. This helps explain the relatively mild susceptibility to viral disease observed in STAT3- and IL-21R-deficient subjects.

摘要

背景

CD8(+)T 细胞控制感染和介导抗肿瘤免疫的能力需要效应细胞和记忆细胞的发育和存活。IL-21 已成为在感染性疾病的小鼠模型中诱导 CD8(+)T 细胞效应功能和记忆细胞发育的有效诱导剂。然而,IL-21 及其相关信号通路在人类受试者保护性 CD8(+)T 细胞免疫中的作用尚不清楚。

目的

我们旨在确定哪些信号通路介导了 IL-21 对人类 CD8(+)T 细胞的影响,以及这些通路的缺陷是否导致 IL-21 信号级联成分突变引起的原发性免疫缺陷患者的疾病发病机制。

方法

由单基因突变引起的人类原发性免疫缺陷为评估特定分子在调节人类淋巴细胞功能中的要求提供了独特的机会。使用来自信号转导和转录激活因子 1(STAT1)、STAT3 或 IL-21 受体(IL21R)功能丧失突变患者的淋巴细胞,评估这些基因在体内和体外对人类 CD8(+)T 细胞分化的各自作用。

结果

STAT3 和 IL21R 突变,但不是 STAT1 突变,导致体内多种记忆 CD8(+)T 细胞亚群减少,表明 STAT3 信号可能在 IL-21R 下游调节记忆细胞池。此外,STAT3 对于诱导 IL-21 刺激的幼稚 CD8(+)T 细胞中的裂解机制很重要。然而,这一缺陷可以通过 T 细胞受体的结合来克服。

结论

IL-21R/STAT3 通路是人类 CD8(+)T 细胞行为的许多方面所必需的,但在某些情况下可以被其他信号所补偿。这有助于解释 STAT3 和 IL-21R 缺陷患者对病毒疾病相对较弱的易感性。

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