Dimitriou Marios, Woll Petter S, Mortera-Blanco Teresa, Karimi Mohsen, Wedge David C, Doolittle Helen, Douagi Iyadh, Papaemmanuil Elli, Jacobsen Sten Eirik W, Hellström-Lindberg Eva
Center for Hematology and Regenerative Medicine, Karolinska Institutet, Department of Medicine, Karolinska University Hospital Huddinge, Stockholm, Sweden.
Haematopoietic Stem Cell Biology Laboratory, MRC Molecular Haematology Unit, Weatherall Institute of Molecular Medicine, University of Oxford, Oxford, United Kingdom.
Oncotarget. 2016 Nov 8;7(45):72685-72698. doi: 10.18632/oncotarget.12234.
The stem and progenitor cell compartments in low- and intermediate-risk myelodysplastic syndromes (MDS) have recently been described, and shown to be highly conserved when compared to those in acute myeloid leukemia (AML). Much less is known about the characteristics of the hematopoietic hierarchy of subgroups of MDS with a high risk of transforming to AML. Immunophenotypic analysis of immature stem and progenitor cell compartments from patients with an isolated loss of the entire chromosome 7 (isolated -7), an independent high-risk genetic event in MDS, showed expansion and dominance of the malignant -7 clone in the granulocyte and macrophage progenitors (GMP), and other CD45RA+ progenitor compartments, and a significant reduction of the LIN-CD34+CD38low/-CD90+CD45RA- hematopoietic stem cell (HSC) compartment, highly reminiscent of what is typically seen in AML, and distinct from low-risk MDS. Established functional in vitro and in vivo stem cell assays showed a poor readout for -7 MDS patients irrespective of marrow blast counts. Moreover, while the -7 clone dominated at all stages of GM differentiation, the -7 clone had a competitive disadvantage in erythroid differentiation. In azacitidine-treated -7 MDS patients with a clinical response, the decreased clonal involvement in mononuclear bone marrow cells was not accompanied by a parallel reduced clonal involvement in the dominant CD45RA+ progenitor populations, suggesting a selective azacitidine-resistance of these distinct -7 progenitor compartments. Our data demonstrate, in a subgroup of high risk MDS with monosomy 7, that the perturbed stem and progenitor cell compartments resemble more that of AML than low-risk MDS.
低危和中危骨髓增生异常综合征(MDS)中的干细胞和祖细胞区室最近已被描述,并且与急性髓系白血病(AML)中的相比,显示出高度保守性。对于具有转化为AML高风险的MDS亚组造血层级的特征,人们了解得要少得多。对孤立性7号染色体完全缺失(孤立性-7)患者的未成熟干细胞和祖细胞区室进行免疫表型分析,孤立性-7是MDS中一个独立的高风险遗传事件,结果显示恶性-7克隆在粒细胞和巨噬细胞祖细胞(GMP)以及其他CD45RA+祖细胞区室中扩增并占主导地位,而LIN-CD34+CD38low/-CD90+CD45RA-造血干细胞(HSC)区室则显著减少,这与AML中通常所见的情况非常相似,且与低危MDS不同。既定的体外和体内干细胞功能检测显示,无论骨髓原始细胞计数如何,-7 MDS患者的检测结果都很差。此外,虽然-7克隆在GM分化的所有阶段都占主导地位,但-7克隆在红系分化中具有竞争劣势。在接受阿扎胞苷治疗且有临床反应的-7 MDS患者中,单核骨髓细胞中克隆参与度的降低并未伴随着占主导地位的CD45RA+祖细胞群体中克隆参与度的平行降低,这表明这些不同的-7祖细胞区室对阿扎胞苷具有选择性抗性。我们的数据表明,在具有7号染色体单体的高风险MDS亚组中,受干扰的干细胞和祖细胞区室与AML的更相似,而不是与低危MDS的相似。