GKT School of Medical Education, King's College London, London, UK.
Department of Old Age Psychiatry, Institute of Psychiatry, Psychology & Neuroscience, King's College London, London, UK.
Int J Geriatr Psychiatry. 2020 May;35(5):436-448. doi: 10.1002/gps.5260. Epub 2020 Jan 16.
Lewy body dementia (LBD) causes more morbidity, disability, and earlier mortality than Alzheimer disease. Molecular mechanisms underlying neurodegeneration in LBD are poorly understood. We aimed to do a systematic review of all genetic association studies that investigated people with LBD for improving our understanding of LBD molecular genetics and for facilitating discovery of novel biomarkers and therapeutic targets for LBD.
We systematically reviewed five online databases (PROSPERO protocol: CRD42018087114) and completed the quality assessment using the quality of genetic association studies tool.
Eight thousand five hundred twenty-one articles were screened, and 75 articles were eligible to be included. Genetic associations of LBD with APOE, GBA, and SNCA variants have been replicated by two or more good quality studies. Our meta-analyses confirmed that APOE-ε4 is significantly associated with dementia with Lewy bodies (pooled odds ratio [POR] = 2.70; 95% CI, 2.37-3.07; P < .001) and Parkinson's disease dementia (POR = 1.60; 95% CI, 1.21-2.11; P = .001). Other reported genetic associations that need further replication include variants in A2M, BCHE-K, BCL7C, CHRFAM7A, CNTN1, ESR1, GABRB3, MAPT, mitochondrial DNA (mtDNA) haplogroup H, NOS2A, PSEN1, SCARB2, TFAM, TREM2, and UCHL1.
The reported genetic associations and their potential interactions indicate the importance of α-synuclein, amyloid, and tau pathology, autophagy lysosomal pathway, ubiquitin proteasome system, oxidative stress, and mitochondrial dysfunction in LBD. There is a need for larger genome-wide association study (GWAS) for identifying more LBD-associated genes. Future hypothesis-driven studies should aim to replicate reported genetic associations of LBD and to explore their functional implications.
路易体痴呆(LBD)比阿尔茨海默病导致更多的发病率、残疾和更早的死亡率。LBD 神经退行性变的分子机制尚未得到很好的理解。我们旨在对所有研究 LBD 患者的遗传关联研究进行系统综述,以提高我们对 LBD 分子遗传学的理解,并为 LBD 的新型生物标志物和治疗靶点的发现提供便利。
我们系统地审查了五个在线数据库(PROSPERO 方案:CRD42018087114),并使用遗传关联研究工具完成了质量评估。
筛选了 8521 篇文章,有 75 篇文章符合纳入标准。已有两项或更多高质量研究证实了 LBD 与 APOE、GBA 和 SNCA 变体的遗传关联。我们的荟萃分析证实 APOE-ε4 与路易体痴呆(合并优势比 [POR] = 2.70;95%置信区间,2.37-3.07;P <.001)和帕金森病痴呆(POR = 1.60;95%置信区间,1.21-2.11;P =.001)显著相关。其他需要进一步复制的报告遗传关联包括 A2M、BCHE-K、BCL7C、CHRFAM7A、CNTN1、ESR1、GABRB3、MAPT、线粒体 DNA(mtDNA)单倍群 H、NOS2A、PSEN1、SCARB2、TFAM、TREM2 和 UCHL1 中的变体。
报告的遗传关联及其潜在相互作用表明,α-突触核蛋白、淀粉样蛋白和 tau 病理学、自噬溶酶体途径、泛素蛋白酶体系统、氧化应激和线粒体功能障碍在 LBD 中具有重要作用。需要进行更大的全基因组关联研究(GWAS)以确定更多与 LBD 相关的基因。未来的假设驱动研究应旨在复制报告的 LBD 遗传关联,并探索其功能意义。