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胚系致病性变异在骨化性乳腺肿瘤患者中的研究进展和 BRCA1 基因的作用

Germline pathogenic variants in metaplastic breast cancer patients and the emerging role of the BRCA1 gene.

机构信息

Division of Breast Surgery, IEO, European Institute of Oncology IRCCS, Milan, Italy.

Department of Oncology and Hemato-Oncology, University of Milan, Milan, Italy.

出版信息

Eur J Hum Genet. 2023 Nov;31(11):1275-1282. doi: 10.1038/s41431-023-01429-2. Epub 2023 Jul 18.

Abstract

Metaplastic breast cancer (MpBC) is a rare, aggressive breast cancer (BC) histotype. Scarce information is available about MpBC genetic predisposition. Previous studies, mainly consisting of case reports, retrospective reviews and others on target therapies, pointed to a possible involvement of the BRCA1 gene in increasing MpBC risk, without ever confirming it. In this study, we retrospectively reviewed all BC patients counseled at our Institute for genetic testing of at least BRCA1 or BRCA2 (BRCA) genes and we found that 23 (23/5226 = 0.4%) were affected by MpBC. About 65% (15/23) of MpBC patients harbored a germline pathogenic variant (PV): 13 in BRCA1 (86.7%), including two patients who received genetic testing for known familial PV, one in TP53 (6.7%), and one in MLH1 (6.7%). We observed a statistically different frequency of MpBC in patients who carried a PV in the BRCA genes (13/1114 = 1.2%) vs. all other BC patients (10/4112 = 0.2%) (p = 0.0002). BRCA carriers proved to have an increased risk of developing MpBC compared to all other BC patients who were tested for BRCA genes (OR = 4.47; 95% CI: 1.95-10.23). Notably, MpBCs were diagnosed in 2.1% (13/610) of BRCA1 carriers. No MpBCs were observed in BRCA2 carriers (0/498 = 0%), revealing a statistically significant difference between the prevalence of MpBCs in BRCA1 and BRCA2 carriers (p = 0.0015). Our results confirmed that BRCA1 is involved in MpBC predisposition. Further studies on unselected patients are needed to elucidate the authentic role of BRCA1 and to explore the possible implication of other genes in MpBC predisposition.

摘要

化生性乳腺癌(MpBC)是一种罕见且侵袭性的乳腺癌(BC)组织学类型。关于 MpBC 遗传易感性的信息很少。以前的研究主要包括病例报告、回顾性综述和针对靶向治疗的研究,指出 BRCA1 基因可能参与增加 MpBC 的风险,但从未得到证实。在这项研究中,我们回顾性地分析了在我们研究所接受至少 BRCA1 或 BRCA2(BRCA)基因遗传检测的所有 BC 患者,发现 23 例(23/5226=0.4%)患有 MpBC。大约 65%(15/23)的 MpBC 患者携带种系致病性变异(PV):13 例在 BRCA1 中(86.7%),包括 2 例接受已知家族性 PV 遗传检测的患者,1 例在 TP53 中(6.7%),1 例在 MLH1 中(6.7%)。我们观察到携带 BRCA 基因中的 PV 的患者中 MpBC 的发生率存在统计学差异(13/1114=1.2%)与所有其他接受 BRCA 基因检测的 BC 患者(10/4112=0.2%)(p=0.0002)。与所有接受 BRCA 基因检测的 BC 患者相比,BRCA 携带者发生 MpBC 的风险增加(OR=4.47;95%CI:1.95-10.23)。值得注意的是,在 2.1%(13/610)的 BRCA1 携带者中诊断出 MpBC。在 BRCA2 携带者中未观察到 MpBC(0/498=0%),BRCA1 和 BRCA2 携带者中 MpBC 的患病率存在统计学显著差异(p=0.0015)。我们的研究结果证实 BRCA1 参与了 MpBC 的易感性。需要对未选择的患者进行进一步的研究,以阐明 BRCA1 的真实作用,并探讨其他基因在 MpBC 易感性中的可能作用。

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本文引用的文献

1
Metaplastic breast cancer: an all-round multidisciplinary consensus.
Eur J Cancer Prev. 2023 Jul 1;32(4):348-363. doi: 10.1097/CEJ.0000000000000794. Epub 2023 May 12.
2
Breast cancer in a teenage girl with BRCA mutation: A case report from a low middle-income country.
Int J Surg Case Rep. 2022 Sep;98:107513. doi: 10.1016/j.ijscr.2022.107513. Epub 2022 Aug 13.
4
Pathology of Tumors Associated With Pathogenic Germline Variants in 9 Breast Cancer Susceptibility Genes.
JAMA Oncol. 2022 Mar 1;8(3):e216744. doi: 10.1001/jamaoncol.2021.6744. Epub 2022 Mar 17.
5
Poor response to neoadjuvant chemotherapy in metaplastic breast carcinoma.
NPJ Breast Cancer. 2021 Jul 22;7(1):96. doi: 10.1038/s41523-021-00302-z.
6
Metaplastic carcinoma of the breast and BRCA1 germline mutation: a case report and review.
Hered Cancer Clin Pract. 2021 Jan 6;19(1):3. doi: 10.1186/s13053-020-00162-x.
7
A comprehensive overview of metaplastic breast cancer: clinical features and molecular aberrations.
Breast Cancer Res. 2020 Nov 4;22(1):121. doi: 10.1186/s13058-020-01353-z.
8
Metaplastic breast cancer: Prognostic and therapeutic considerations.
J Surg Oncol. 2021 Jan;123(1):61-70. doi: 10.1002/jso.26248. Epub 2020 Oct 12.
9
The genetic landscape of metaplastic breast cancers and uterine carcinosarcomas.
Mol Oncol. 2021 Apr;15(4):1024-1039. doi: 10.1002/1878-0261.12813. Epub 2021 Feb 19.
10
Guidelines for the Li-Fraumeni and heritable TP53-related cancer syndromes.
Eur J Hum Genet. 2020 Oct;28(10):1379-1386. doi: 10.1038/s41431-020-0638-4. Epub 2020 May 26.

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