Children's Hospital, University of Mainz, Dept. Lysosomal Storage Disorders, Langenbeckstrasse 1, 55101 Mainz, Germany.
IUBMB Life. 2010 Jan;62(1):33-40. doi: 10.1002/iub.284.
In the last years, much progress has been achieved in the field of lysosomal storage disorders. In the past, no specific treatment was available for the affected patients; management mainly consisted of supportive care and treatment of complications. As orphan drug regulations, however, encouraged development of drugs for these disorders by granting marketing exclusivity for 10 years and other commercial benefits, enzyme replacement therapy became available for lysosomal storage disorders, such as Gaucher disease, Fabry disease, mucopolysaccharidoses type I, II, and VI, and Pompe disease. This review will summarize the efficacy and clinical status of hematopoietic stem cell transplantation, enzyme replacement, and substrate deprivation therapy, and describe new therapeutic perspectives currently under preclinical investigations such as chaperone-mediated therapy, stop-codon read-through therapy, and gene therapy.
在过去的几年中,溶酶体贮积症领域取得了很大进展。过去,受影响的患者没有特定的治疗方法;治疗主要包括支持性护理和并发症的治疗。然而,随着孤儿药法规的实施,通过给予 10 年的市场独占权和其他商业利益,鼓励开发这些疾病的药物,溶酶体贮积症(如戈谢病、法布雷病、黏多糖贮积症 I、II 和 VI 型以及庞贝病)的酶替代疗法已经问世。这篇综述将总结造血干细胞移植、酶替代和底物剥夺疗法的疗效和临床状况,并描述目前在临床前研究中的新治疗前景,如伴侣介导的治疗、终止密码子通读治疗和基因治疗。